Affinage

PACS2

Phosphofurin acidic cluster sorting protein 2 · UniProt Q86VP3

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Length
889 aa
Mass
97.7 kDa
Annotated
2026-04-29
55 papers in source corpus 20 papers cited in narrative 20 extracted findings

Mechanistic narrative

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Mechanism profile

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Evidence

Reading pass · 20 per-paper findings extracted from the source corpus
Year Finding Method Journal Conf PMIDs
2005 PACS-2 controls the apposition of mitochondria with the ER; depletion of PACS-2 causes BAP31-dependent mitochondria fragmentation and uncoupling from the ER. PACS-2 also translocates Bid to mitochondria in response to apoptotic inducers, triggering truncated Bid formation, cytochrome c release, and caspase-3 activation. siRNA knockdown, subcellular fractionation, fluorescence microscopy, co-immunoprecipitation, cell death assays The EMBO journal High 15692567
2008 PACS-2 interacts with calnexin's cytosolic domain to sort calnexin between the rough ER, mitochondria-associated membrane (MAM), and plasma membrane. Phosphorylation of calnexin Ser554/564 by CK2 reduces its binding to PACS-2, redirecting calnexin to the cell surface. siRNA knockdown, co-immunoprecipitation, phosphomimetic mutagenesis, immunofluorescence, flow cytometry Molecular biology of the cell High 18417615
2008 HIV-1 Nef binds PACS-2 via Nef EEEE65, which targets Nef to the paranuclear/TGN region, enabling PXXP75 to activate a TGN-localized Src family kinase (SFK)–ZAP70–PI3K cascade required for MHC-I down-regulation. Genetic loss of PACS-2 (Pacs-2−/− splenocytes and fibroblasts) prevents Nef paranuclear localization and MHC-I internalization. Co-immunoprecipitation, siRNA knockdown, Pacs-2 knockout mouse cells, fluorescence microscopy, kinase assays The Journal of biological chemistry High 18296443
2009 PACS-2 is phosphorylated at Ser437 in vivo by Akt; phospho-Ser437 binds 14-3-3 with high affinity, which represses PACS-2 apoptotic activity while maintaining its membrane-trafficking function. TRAIL triggers Ser437 dephosphorylation, switching PACS-2 from a homeostatic to a pro-apoptotic state. In vivo phosphorylation mapping, pharmacological Akt inhibition, genetic Akt studies, 14-3-3 co-immunoprecipitation, TRAIL cytotoxicity assays, mouse hepatocyte infection model Molecular cell High 19481529
2012 PACS-2 and PACS-1 interact with Nef via a bipartite site formed by Nef EEEE65 (N-terminal domain) and W113 (core domain) binding to a cargo subsite on PACS-1/PACS-2. This interaction occurs on Rab5- and Rab7-positive endosomes (visualized by bimolecular fluorescence complementation) and is required for Nef-induced MHC-I down-regulation. Bimolecular fluorescence complementation, co-immunoprecipitation, site-directed mutagenesis, MHC-I surface assay in PBMCs Molecular biology of the cell High 22496420
2012 TRAIL induces recruitment of PACS-2 to DR5-positive endosomes where it forms a complex with Bim and Bax on lysosomal membranes, promoting lysosomal membrane permeabilization and cathepsin B release. In vitro, recombinant PACS-2 binds Bim directly but not Bax; Bim is required for subsequent Bax recruitment. shRNA knockdown, co-immunoprecipitation, in vitro binding assay with recombinant proteins, lysosomal membrane permeabilization assay, clonogenic survival The Journal of biological chemistry High 22645134
2014 PACS-2 shuttles from the cytoplasm to the nucleus where it interacts with SIRT1 and directly inhibits SIRT1-catalyzed p53 deacetylation, thereby sustaining p53 acetylation and p21 induction required for DNA-damage-induced cell-cycle arrest. Pacs-2−/− thymocytes show reduced p53 acetylation and blunted p21 induction. In vitro SIRT1 deacetylation assay, co-immunoprecipitation, Pacs-2 knockout mouse thymocytes, SIRT1 inhibitor rescue, subcellular fractionation Cell reports High 25159152
2014 cIAP-1 and cIAP-2 directly bind PACS-2 and mediate K48-linked poly-ubiquitination of PACS-2, targeting it for proteasomal degradation. Dual cIAP knockout reduces PACS-2 ubiquitination, elevates PACS-2 levels, and sensitizes cells to TRAIL-induced lysosomal membrane permeabilization in a PACS-2-dependent manner. Cell-free ubiquitination assay, co-immunoprecipitation, single and double c-Iap knockout mouse hepatocytes, cycloheximide chase PloS one High 24633224
2015 PACS-2 co-localizes with ADAM17 on early endosomes and is required for recycling of internalized ADAM17 away from degradative pathways back to the cell surface. PACS-2 loss reduces ADAM17 cell-surface levels, ADAM17-dependent ErbB ligand shedding, and EGFR signaling; Pacs2−/− mice show reduced phospho-EGFR and intestinal proliferation. Genome-wide siRNA screen, confocal co-localization, ADAM17 recycling assay, Pacs2 knockout mice, EGFR phosphorylation assay Nature communications High 26108729
2016 Cytoplasmic PACS-2 interacts with ATM to drive NF-κB activation and induction of anti-apoptotic Bcl-xL following DNA damage. Pacs-2−/− thymocytes show blunted Bcl-xL induction, increased mitochondrial outer membrane permeabilization, and accelerated apoptosis after genotoxic stress; PACS-2 is not required for TNFα-induced NF-κB activation. Co-immunoprecipitation, Pacs-2 knockout mouse thymocytes, mitochondrial membrane permeabilization assay, NF-κB reporter, western blot Cell death and differentiation High 26943323
2018 PACS-2 engages an insulin-responsive sensor in the SIRT1 N-terminal disordered region comprising an acidic cluster (AC) and a 3-helix bundle (3HB). DBC1 removes a distal shield from the 3HB, permitting PACS-2 to engage the AC and transiently exposed helix 3, disrupting 3HB structure and inhibiting SIRT1 catalysis. The SIRT1 activator SRT1720 stabilizes the 3HB and protects SIRT1 from PACS-2-mediated inhibition. NMR structural analysis, in vitro SIRT1 deacetylation assay, co-immunoprecipitation, mutagenesis, STAC binding assay Molecular cell High 30415949
2018 The recurrent PACS-2 E209K missense variant reduces the ability of the autoregulatory domain to modulate the interaction between the PACS-2 FBR (cargo-binding region) and client proteins, potentially disturbing cellular trafficking and causing developmental epileptic encephalopathy. Functional binding assay comparing WT and E209K FBR-client interactions, whole-exome sequencing in 14 individuals American journal of human genetics Medium 29656858
2019 PACS-2 knockdown impairs mitophagosome formation and mitophagy in vascular smooth muscle cells; increased MAM contacts and PACS-2-associated MAMs are observed upon atherogenic lipid stimulation, and disrupting MAMs via PACS-2 loss potentiates VSMC apoptosis. High-resolution confocal microscopy, proximity ligation assay, siRNA knockdown, mitophagy flux assay, apoptosis assay Cells Medium 31242668
2019 PACS2 promotes MAM formation and mitochondrial Ca2+ transfer in endothelial cells; ox-LDL increases PACS2 localization at mitochondria and ER-mitochondria contacts, and silencing PACS2 inhibits ox-LDL-induced mitochondrial Ca2+ elevation, ROS production, MMP loss, cytochrome c release, and apoptosis. siRNA knockdown, confocal microscopy of MAM contacts, mitochondrial Ca2+ measurement, ROS/MMP/cytochrome c assays Experimental cell research Medium 30970236
2022 PACS-2 interacts with BECN1 (Beclin-1) and mediates its relocalization to MAM, where BECN1 promotes mitophagosome formation. PACS-2 overexpression blocks mitochondrial DRP1 recruitment, reducing excessive mitochondrial fission and restoring mitophagy in high-glucose conditions. Co-immunoprecipitation, proximity ligation assay, confocal microscopy, conditional Pacs-2 knockout mice, PACS-2 overexpression in HK-2 cells, mitophagy flux assay Diabetes High 35133431
2022 PACS2 interacts with TRPV1; reduced PACS2 levels during ER stress are influenced by this interaction, and restoration of PACS2 via TRPV1-modulating drug capsaicin reduces ER-mitochondria uncoupling and alveolar epithelial apoptosis in IPF models. Co-immunoprecipitation, confocal microscopy, overexpression/knockdown in AEC2 cells, precision-cut lung slices from IPF patients, apoptosis assay Cellular and molecular life sciences Medium 35212819
2022 PACS-2 E209K mutation increases the protein's half-life (slower turnover), increases association with 14-3-3ε, and increases susceptibility to staurosporine-induced apoptosis compared to wild-type PACS-2. Cycloheximide chase, co-immunoprecipitation, staurosporine apoptosis assay in HCT116 cells ACS omega Medium 36188273
2023 PACS-2 interacts with transcription factor EB (TFEB) and promotes its nuclear translocation, which activates expression of the ER-phagy receptor FAM134B, thereby facilitating ER-phagy in renal tubular cells. Co-immunoprecipitation, nuclear fractionation, PACS-2 overexpression and siRNA knockdown, FAM134B siRNA rescue, Pacs-2 proximal tubule-specific KO mice Cell death & disease Medium 37794057
2024 PACS-2 suppresses phosphorylation and nuclear translocation of SP1, thereby downregulating LRRK2 expression. Reduced LRRK2 decreases ubiquitination and degradation of Mfn2 via the JNK pathway, preserving MAM integrity and nucleus pulposus stem cell survival. Co-immunoprecipitation, western blot, Pacs-2 knockout mice, overexpression studies, ubiquitination assay Advanced science Medium 41190767
2024 PACS-2 is required for CCHFV glycoprotein (Gn and Gc) trafficking through the retrograde network; loss of PACS-2 impairs CCHFV assembly and release of infectious viral particles. Infection assays, biochemical trafficking assays, confocal microscopy in virus-producing cells, siRNA knockdown Emerging microbes & infections Medium 38661085

Source papers

Stage 0 corpus · 55 papers · ranked by NIH iCite citations
Year Title Journal Citations PMID
2005 PACS-2 controls endoplasmic reticulum-mitochondria communication and Bid-mediated apoptosis. The EMBO journal 492 15692567
2008 The subcellular distribution of calnexin is mediated by PACS-2. Molecular biology of the cell 188 18417615
2014 miR-499 protects cardiomyocytes from H 2O 2-induced apoptosis via its effects on Pdcd4 and Pacs2. RNA biology 108 24646523
2022 PACS-2 Ameliorates Tubular Injury by Facilitating Endoplasmic Reticulum-Mitochondria Contact and Mitophagy in Diabetic Nephropathy. Diabetes 81 35133431
2019 The Multifunctional Sorting Protein PACS-2 Controls Mitophagosome Formation in Human Vascular Smooth Muscle Cells through Mitochondria-ER Contact Sites. Cells 75 31242668
2020 PACS-2: A key regulator of mitochondria-associated membranes (MAMs). Pharmacological research 74 32673704
2008 HIV-1 Nef binds PACS-2 to assemble a multikinase cascade that triggers major histocompatibility complex class I (MHC-I) down-regulation: analysis using short interfering RNA and knock-out mice. The Journal of biological chemistry 73 18296443
2014 The multifunctional sorting protein PACS-2 regulates SIRT1-mediated deacetylation of p53 to modulate p21-dependent cell-cycle arrest. Cell reports 69 25159152
2009 Akt and 14-3-3 control a PACS-2 homeostatic switch that integrates membrane traffic with TRAIL-induced apoptosis. Molecular cell 66 19481529
2001 Effect of postoperative atrial fibrillation on length of stay after cardiac surgery (The Postoperative Atrial Fibrillation in Cardiac Surgery study [PACS(2)]. The American journal of cardiology 65 11274944
2019 PACS2 is required for ox-LDL-induced endothelial cell apoptosis by regulating mitochondria-associated ER membrane formation and mitochondrial Ca2+ elevation. Experimental cell research 58 30970236
2018 A Recurrent De Novo PACS2 Heterozygous Missense Variant Causes Neonatal-Onset Developmental Epileptic Encephalopathy, Facial Dysmorphism, and Cerebellar Dysgenesis. American journal of human genetics 57 29656858
2012 An interdomain binding site on HIV-1 Nef interacts with PACS-1 and PACS-2 on endosomes to down-regulate MHC-I. Molecular biology of the cell 57 22496420
2021 PACS-2 attenuates diabetic kidney disease via the enhancement of mitochondria-associated endoplasmic reticulum membrane formation. Cell death & disease 52 34836936
2012 Tumor necrosis factor-related apoptosis-inducing ligand (TRAIL) protein-induced lysosomal translocation of proapoptotic effectors is mediated by phosphofurin acidic cluster sorting protein-2 (PACS-2). The Journal of biological chemistry 47 22645134
2015 The sorting protein PACS-2 promotes ErbB signalling by regulating recycling of the metalloproteinase ADAM17. Nature communications 45 26108729
2018 An Insulin-Responsive Sensor in the SIRT1 Disordered Region Binds DBC1 and PACS-2 to Control Enzyme Activity. Molecular cell 41 30415949
2016 PACS-2 mediates the ATM and NF-κB-dependent induction of anti-apoptotic Bcl-xL in response to DNA damage. Cell death and differentiation 30 26943323
2024 PACS2/CPT1A/DHODH signaling promotes cardiomyocyte ferroptosis in diabetic cardiomyopathy. Cardiovascular diabetology 29 39633391
2022 Ferulic acid attenuates high glucose-induced MAM alterations via PACS2/IP3R2/FUNDC1/VDAC1 pathway activating proapoptotic proteins and ameliorates cardiomyopathy in diabetic rats. International journal of cardiology 27 36481261
2014 Cellular inhibitor of apoptosis (cIAP)-mediated ubiquitination of phosphofurin acidic cluster sorting protein 2 (PACS-2) negatively regulates tumor necrosis factor-related apoptosis-inducing ligand (TRAIL) cytotoxicity. PloS one 27 24633224
2022 PACS2-TRPV1 axis is required for ER-mitochondrial tethering during ER stress and lung fibrosis. Cellular and molecular life sciences : CMLS 25 35212819
2022 PACS-2 deficiency in tubular cells aggravates lipid-related kidney injury in diabetic kidney disease. Molecular medicine (Cambridge, Mass.) 25 36138342
2023 PACS-2 deficiency aggravates tubular injury in diabetic kidney disease by inhibiting ER-phagy. Cell death & disease 22 37794057
2019 Expanding the clinical spectrum associated with PACS2 mutations. Clinical genetics 19 30684285
2022 AKT/PACS2 Participates in Renal Vascular Hyperpermeability by Regulating Endothelial Fatty Acid Oxidation in Diabetic Mice. Frontiers in pharmacology 13 35865947
2023 Mitochondria-associated membrane protein PACS2 maintains right cardiac function in hypobaric hypoxia. iScience 11 36968068
2020 Coloboma may be a shared feature in a spectrum of disorders caused by mutations in the WDR37-PACS1-PACS2 axis. American journal of medical genetics. Part A 11 33369122
2024 Renal denervation improves mitochondrial oxidative stress and cardiac hypertrophy through inactivating SP1/BACH1-PACS2 signaling. International immunopharmacology 9 39173402
2022 The Phosphofurin Acidic Cluster Sorting Protein 2 (PACS-2) E209K Mutation Responsible for PACS-2 Syndrome Increases Susceptibility to Apoptosis. ACS omega 9 36188273
2022 First reported case of an inherited PACS2 pathogenic variant with variable expression. Epileptic disorders : international epilepsy journal with videotape 7 35770754
2019 MAP‑1B, PACS‑2 and AHCYL1 are regulated by miR‑34A/B/C and miR‑449 in neuroplasticity following traumatic spinal cord injury in rats: Preliminary explorative results from microarray data. Molecular medicine reports 7 31432119
2021 [Early infantile epileptic encephalopathy caused by PACS2 gene variation: three cases report and literature review]. Zhonghua er ke za zhi = Chinese journal of pediatrics 6 34405643
2025 PACS2 initiates foam cell formation in macrophages through the ROS-PPARγ-CD36 positive feedback loop. Biochemical pharmacology 5 40653022
2022 Knockdown of circ_0002194 protects against oxidized low-density lipoprotein-induced cell damage via the regulation of the miR-637/PACS2 axis in human vascular endothelial cells. Interactive cardiovascular and thoracic surgery 5 35951762
2017 Loss of PACS-2 delays regeneration in DSS-induced colitis but does not affect the ApcMin model of colorectal cancer. Oncotarget 5 29312533
2024 PACS-1 variant protein is aberrantly localized in Caenorhabditis elegans model of PACS1/PACS2 syndromes. Genetics 4 39031646
2021 Vein of Galen aneurysm, dilated cardiomyopathy, and slender habitus in a patient with a recurrent pathogenic variant in PACS2. American journal of medical genetics. Part A 4 34894068
2025 PACS2/PKCα/NOX4 pathway damaged the renal vascular endothelial barrier by promoting ROS production in diabetic nephropathy mice. Molecular and cellular biochemistry 3 40775117
2023 Long-Term Outcome of Neonatal Seizure with PACS2 Mutation: Case Series and Literature Review. Children (Basel, Switzerland) 3 37189870
2022 First Report of Mexican Patients with PACS1-Related Neurodevelopmental Disorder and Review of the PACS1-, PACS2-, and WDR37-Related Ophthalmological Manifestations. Molecular syndromology 2 37064331
2025 AI-Based Facial Phenotyping Supports a Shared Molecular Axis in PACS1-, PACS2-, and WDR37-Related Syndromes. International journal of molecular sciences 1 40869285
2025 PACS-2 Mitigates NPSC Apoptosis and Intervertebral Disc Degeneration by Preserving MAM Integrity via the SP1/LRRK2/Mfn2 Axis. Advanced science (Weinheim, Baden-Wurttemberg, Germany) 1 41190767
2024 A missense variant in the PACS2 gene cause Epileptic Encephalopathy and seizures in Saudi family. Pakistan journal of medical sciences 1 38545008
2024 PACS2, PACS1, and VACTERL: A Clinical Overlap. Molecular syndromology 1 39911171
2023 PACS2 pathogenic variant associated with malformation of cortical development and epilepsy. Epileptic disorders : international epilepsy journal with videotape 1 38031819
2021 [Clinical and genetic analysis of PACS2 gene variant in two child patients with developmental and epileptic encephalopathy 66]. Zhonghua yi xue yi chuan xue za zhi = Zhonghua yixue yichuanxue zazhi = Chinese journal of medical genetics 1 34625934
2026 MiR-499-5P/PACS2/TRPV1 Axis Maintains Mitochondrial Homeostasis and Left Ventricular Function after Extreme Cold Stress. Journal of cardiovascular translational research 0 41644764
2026 PACS2 deficiency ameliorates hepatic steatosis via inhibition of the JNK signaling pathway in diabetic mice. Biochemical pharmacology 0 41687826
2026 Quercetin Alleviates Endothelial Dysfunction in Atherosclerosis by Inhibiting Ferroptosis Through PACS2/HMOX-1 Pathway. The American journal of Chinese medicine 0 41692703
2026 Crebanine attenuates copper neurotoxicity via PACS-2 upregulation and TXNIP/TRPV1 axis suppression. Neurotoxicology 0 41962777
2024 Characteristics of Developmental and Epileptic Encephalopathy Associated with PACS2 p.Glu209Lys Pathogenic Variant-Our Experience and Systematic Review of the Literature. Biomolecules 0 38540691
2024 The PACS-2 protein and trafficking motifs in CCHFV Gn and Gc cytoplasmic domains govern CCHFV assembly. Emerging microbes & infections 0 38661085
2024 PACS-1 variant protein is aberrantly localized in C. elegans model of PACS1/PACS2 syndromes. bioRxiv : the preprint server for biology 0 38712144
2024 Understanding PACS2 syndrome's pathomechanism by studying E209K and E211K mutations. Mammalian genome : official journal of the International Mammalian Genome Society 0 39738582